EUROPEAN UROLOGY 65 (2014) 1058–1066 available at www.sciencedirect.com journal homepage: www.europeanurology.com Platinum Priority – Prostate Cancer Editorial by Brian F. Chapin, Sean E. McGuire and Ana Aparicio on pp. 1067–1068 of this issue Might Men Diagnosed with Metastatic Prostate Cancer Benefit from Definitive Treatment of the Primary Tumor? A SEER-Based Study Stephen H. Culp a,*, Paul F. Schellhammer b, Michael B. Williams b a Department of Urology, University of Virginia, Charlottesville, VA, USA; b Department of Urology, Eastern Virginia Medical School, Norfolk, VA, USA Article info Abstract Article history: Accepted November 8, 2013 Published online ahead of print on November 20, 2013 Background: Few data exist regarding the impact on survival of definitive treatment of the prostate in men diagnosed with metastatic prostate cancer (mPCa). Objective: To evaluate the survival of men diagnosed with mPCa based on definitive treatment of the prostate. Design, setting, and participants: Men with documented stage IV (M1a–c) PCa at diagnosis identified using Surveillance Epidemiology and End Results (SEER) (2004–2010) and divided based on definitive treatment of the prostate (radical prostatectomy [RP] or brachytherapy [BT]) or no surgery or radiation therapy (NSR). Outcome measurements and statistical analysis: Kaplan-Meier methods were used to calculate overall survival (OS). Multivariable competing risks regression analysis was used to calculate disease-specific survival (DSS) probability and identify factors associated with cause-specific mortality (CSM). Results and limitations: A total of 8185 patients were identified: NSR (n = 7811), RP (n = 245), and BT (n = 129). The 5-yr OS and predicted DSS were each significantly higher in patients undergoing RP (67.4% and 75.8%, respectively) or BT (52.6 and 61.3%, respectively) compared with NSR patients (22.5% and 48.7%, respectively) ( p < 0.001). Undergoing RP or BT was each independently associated with decreased CSM ( p < 0.01). Similar results were noted regardless of the American Joint Committee on Cancer (AJCC) M stage. Factors associated with increased CSM in patients undergoing local therapy included AJCC T4 stage, high-grade disease, prostate-specific antigen 20 ng/ml, age 70 yr, and pelvic lymphadenopathy ( p < 0.05). The major limitation of this study was the lack of variables from SEER known to influence survival of patients with mPCa, including treatment with systemic therapy. Conclusions: Definitive treatment of the prostate in men diagnosed with mPCa suggests a survival benefit in this large population-based study. These results should serve as a foundation for future prospective trials. Patient summary: We used a large population-based cancer database to examine survival in men diagnosed with metastatic prostate cancer (mPCa) undergoing definitive therapy for the prostate. Local therapy (LT) appeared to confer a survival benefit. Therefore, we conclude that prospective trials are needed to further evaluate the role of LT in mPCa. # 2013 European Association of Urology. Published by Elsevier B.V. All rights reserved. Keywords: Metastatic prostate cancer Radical prostatectomy Brachytherapy Outcomes assessment * Corresponding author. Box 800422, Charlottesville, VA 22908, USA. Tel. +1 434 243 9325; Fax: +1 434 982 3652. E-mail address: shc5e@virginia.edu (S.H. Culp). 0302-2838/$ – see back matter # 2013 European Association of Urology. Published by Elsevier B.V. All rights reserved. http://dx.doi.org/10.1016/j.eururo.2013.11.012 1059 EUROPEAN UROLOGY 65 (2014) 1058–1066 1. prostate—either surgical removal or radiotherapy—on survival in men diagnosed with mPCa using a large population-based cancer database. Introduction Surgery or radiation therapy are standard treatment options for men diagnosed with organ-confined prostate cancer (PCa) and a life expectancy 10 yr [1]. For locally advanced disease, radiation therapy with androgendeprivation therapy (ADT) is more commonly used. However, for patients with metastatic disease at the time of diagnosis, ADT remains the initial management choice [2]. Despite data demonstrating improved survival with tumor burden reduction in other malignancies [3–5], including treatment of the primary tumor itself [6–9], little data exist for men diagnosed with metastatic PCa (mPCa). The purpose of this study, therefore, was to examine the impact of definitive local therapy (LT) of the 2. Methods Cases were identified from the Surveillance Epidemiology and End Results (SEER) database. SEER encompasses population-based cancer registries covering approximately 28% of the US population and records basic demographics, tumor site, histology, stage, grade, and treatments performed. Because the mortality status of most all cases is known, survival time can be accurately determined [10]. Cases were identified as any man 35 yr diagnosed with malignant adenocarcinoma (International Classification of Diseases for Oncology, third edition, code 8140) of the prostate (site code 61.9) between 2004 Table 1 – Patient characteristics Characteristic Median age, yr (IQR)^ Race, no. (%) White African American Other Year of diagnosis, no. (%) 2004 2005 2006 2007 2008 2009 2010 Marital status, no. (%)^ Single/widowed/divorced Married Unknown PSA, ng/ml, no. (%)^ <10 10–19 20–29 30 Unknown Tumor grade^ Low to moderate High Unknown AJCC T stage, no. (%)^ T1/T2 T3/T4 Unknown AJCC N stage, no. (%)^ N0 N1 Unknown AJCC M stage, no. (%)^ M1a M1b M1c EBRT received, no. (%) No surgery or radiation therapy (n = 7811) 72 (63–80) 5670 (72.6) 1570 (20.1) 571 (7.3) Radical prostatectomy (n = 245) 62 (58–67) p valuea Brachytherapy (n = 129) p valueb p valuec <0.001 0.514 68 (61–74) <0.001 0.633 <0.001 0.756 0.004 0.007 0.086 <0.001 <0.001 <0.001 <0.001 <0.001 0.002 <0.001 <0.001 <0.001 0.002 <0.001 <0.001 <0.001 186 (75.9) 43 (17.6) 16 (6.5) 91 (70.5) 30 (23.3) 8 (6.2) 0.129 938 957 943 1129 1262 1276 1306 (95.2) (96.2) (93.7) (95.5) (94.5) (95.4) (97.0) 29 23 33 33 51 47 29 (3.0) (2.3) (3.3) (2.8) (3.8) (3.5) (2.2) 15 15 30 20 22 15 12 (1.5) (1.5) (3.0) (1.7) (1.7) (1.1) (0.9) <0.001 1673 (25.2) 4375 (66.0) 584 (8.8) 26 (11.7) 184 (82.5) 13 (5.8) 632 871 558 4815 935 115 50 17 32 31 19 (16.7) 86 (75.4) 9 (7.9) <0.001 (8.1) (11.2) (7.1) (61.6) (12.0) (46.9) (20.4) (6.9) (13.1) (12.7) 45 19 11 44 10 (34.9) (14.7) (8.5) (34.1) (7.8) <0.001 439 (5.6) 5673 (72.6) 1699 (21.8) 51 (20.8) 187 (76.3) 7 (2.9) 4318 (55.3) 1562 (20.0) 1931 (24.7) 130 (53.1) 113 (46.1) 2 (0.8) 3807 (48.7) 1514 (19.4) 2490 (31.9) 165 (67.4) 68 (27.8) 12 (4.9) 463 5469 1879 0 24 150 71 41 24 (18.6) 94 (72.9) 11 (8.5) <0.001 91 (70.5) 20 (15.5) 18 (14.0) <0.001 89 (69.9) 17 (13.2) 23 (17.8) 0.004 (5.9) (70.0) (24.1) (0) (9.8) (61.2) (29.0) (16.7) <0.001 16 75 38 54 (12.4) (58.1) (29.5) (41.9) IQR = interquartile range; PSA = prostate-specific antigen; AJCC = American Joint Committee on Cancer; M1a = nonregional lymph nodes; M1b = bone metastasis with or without lymph nodes; M1c = distant metastasis with or without bone and/or lymph node involvement; EBRT = external-beam radiation therapy; NSR = no surgery or radiation therapy; RP = radical prostatectomy; BT = brachytherapy. ^ At the time of diagnosis. a Comparing NSR with RP patients. b Comparing NSR with BT patients. c Comparing NSR with the entire local therapy cohort. 1060 EUROPEAN UROLOGY 65 (2014) 1058–1066 [(Fig._1)TD$IG] and 2010 using all 18 SEER-based registries. Only patients with documented stage IV (M1a–c) disease at the time of diagnosis based on the American Joint Committee on Cancer (AJCC) Cancer Staging Manual, sixth edition, with either radiographic or pathologic confirmation of metastatic disease through the Collaborative Staging System, were included [11]. Per SEER coding guidelines, age, marital status, disease grade (low–moderate [Gleason score 7] or high [Gleason 8]), and clinical AJCC T, N, and M stages were based on data obtained at the time of diagnosis. Furthermore, the prostate-specific antigen (PSA) measurement for each patient corresponded to the highest PSA value recorded prior to diagnostic prostate biopsy and treatment. For each subject, race was defined as white, African American, or other, and cause of death (PCa or non-PCa) was based on the SEER cause-of-death classification. Cases were grouped based on no surgery or radiation therapy (NSR) or definitive LT to the prostate (either radical prostatectomy [RP] [surgery site codes 50 or 70] or brachytherapy [BT] [radiation-specific codes 2, 3, or 4]). Within the LT group, men were not excluded if they received adjuvant external-beam radiation therapy (EBRT). Cases diagnosed by autopsy or death certificate only or with unknown radiation therapy, surgery, or metastatic site were excluded. Patients treated with endoscopic therapy (eg, cryotherapy, transurethral resection) (n = 1312) or EBRT only (n = 2628) were excluded, since these treatments did not coincide with the a priori definition of definitive LT, the latter based on the lack of EBRT organ site–specific codes within SEER. Incidentally, on initial analyses, survival in these patient groups was inferior to NSR patients, possibly suggesting that these treatments were used in a more palliative setting (eg, bone pain, urinary obstruction). Outcomes of interest included overall survival (OS) and diseasespecific survival (DSS), as well as factors independently associated with Fig. 1 – (A) Overall survival and (B) cumulative incidence of prostate cancer (PCa)-specific mortality in patients with metastatic PCa at diagnosis based on treatment received. For cumulative incidence of cancer-specific mortality, analyses are adjusted for age at diagnosis; race; initial prostate-specific antigen; tumor grade; American Joint Committee on Cancer T, N, and M stages; year of diagnosis; and registry, and account for the competing risk of non-PCa death. NSR = no surgery or radiation therapy; RP = radical prostatectomy; BT = brachytherapy. cause-specific mortality (CSM). Kaplan-Meier methods were used to determine OS. Even with mPCa, patients can live many years after diagnosis and may die from non-PCa causes. To account for this situation, competing risks regression analysis, according to the model of Fine and Gray [12], was used to calculate the cumulative incidence of PCa-specific death and DSS probabilities using death from non-PCa as the competing variable. Stepwise multivariable competing risks regression analysis was used to identify factors independently associated with CSM using backward elimination of variables based on the Wald test and a p value 0.20. Variables differing among patient groups were determined using Pearson chi-square analysis. STATA v.12 (Stata Corp, College Station, TX, USA) was used for all analyses, with a p value 0.05 considered significant. 3. Results A total of 8185 eligible cases were identified, with a median follow-up of 16 mo (interquartile range [IQR]: 7–31): NSR (n = 7811), RP (n = 245), and BT (n = 129). Patient characteristics are listed in Table 1. A total of 3115 patients (38.1%) died of PCa: 3048 NSR patients (40.7%), 33 RP patients (13.5%), and 34 BT patients (26.4%). The 5-yr OS was significantly higher in patients undergoing either RP (67.4%; 95% confidence interval [CI], 58.7–74.7) or BT (52.6%; 95% CI, 39.8–63.9) compared with NSR patients (22.5%; 95% CI, 21.1–23.9) ( p < 0.001) (Fig. 1). In addition, undergoing RP or BT was each independently associated with decreased CSM, with predicted 5-yr DSS probabilities of 75.8% and 61.3%, respectively, compared with 48.7% for NSR patients (Fig. 1 and Table 2). In patients dying of nonPCa causes (1284 patients [15.7%]), no significant differences in survival were noted among groups. Although OS was higher in RP patients compared with BT patients, there was no significant difference in CSM between the two groups (Fig. 1). To account for patients who might benefit least from LT—either because of progressive disease, significant comorbidity, or a history of other primary malignancies that might bias outcomes—analyses were repeated, but this time excluding patients dying 12 mo from diagnosis (n = 1813) or with multiple malignant primaries (n = 618). At a median follow-up of 27 mo (IQR: 18–42), 5-yr OS continued to be higher in patients undergoing RP (76.5%; 95% CI, 67.0–83.7) or BT (58.2%; 95% CI, 44.5–69.7) compared with NSR patients (30.6%; 95% CI, 28.9–32.4) ( p < 0.001). Additionally, undergoing RP (subhazard ratio [SHR]: 0.37; 95% CI, 0.26–0.54; p < 0.001) or BT (SHR: 0.57; 95% CI, 0.37–0.87; p = 0.01) was still each independently associated with decreased CSM compared with NSR patients, with 5-yr DSS probabilities of 75.1%, 64.5%, and 46.9%, respectively. Factors independently associated with increased CSM in LT patients included age 70 yr, cT4 disease, PSA 20 ng/ml, high-grade disease, and pelvic lymphadenopathy (Table 3). Five-year OS (77.3%; 95% CI, 67.4–84.5) and DSS probability (89.9%) were highest in patients with one or fewer factors (n = 181 [48.4%]). Although patients with two factors (n = 116 [31.0%]) exhibited lower 5-yr OS (53.1%; 95% CI, 38.9–65.4) and lower DSS probability (68.7%), survival was still better than for NSR patients. However, patients with three or more factors (n = 77 [20.6%]) demonstrated a 5-yr EUROPEAN UROLOGY 65 (2014) 1058–1066 [(Fig._2)TD$IG] 1061 Table 2 – Stepwise multivariable competing risks regression analysis of patients with metastatic prostate cancer at diagnosis* Characteristic Adjusted SHR Type of treatment No surgery or radiation therapy Radical prostatectomy Brachytherapy High-grade disease^ T4 disease^ (vs <T4 disease) PSA 20 ng/ml^ (vs PSA <20 ng/ml) AJCC N stage^ N0 N1 AJCC M stage^ M1a M1b M1c Year of diagnosis 95% confidence interval p value 0.38 0.68 1.70 1.25 0.27–0.53 0.49–0.93 1.42–2.04 1.12–1.40 <0.001 0.018 <0.001 <0.001 1.29 1.20–1.40 <0.001 Ref 1.21 1.09–1.33 <0.001 Ref 1.86 2.35 0.93 1.55–2.24 1.94–2.85 0.91–0.95 <0.001 <0.001 <0.001 Ref SHR = subhazard ratio; PSA = prostate-specific antigen; AJCC = American Joint Committee on Cancer; Ref = reference; M1a = nonregional lymph nodes; M1b = bone metastasis with or without lymph nodes; M1c = distant metastasis with or without bone and lymph node involvement. * Surveillance Epidemiology and End Results, 2004–2010. ^ At the time of diagnosis. Table 3 – Stepwise multivariable competing risks regression analysis of patients with metastatic prostate cancer at diagnosis undergoing definitive local therapy of the prostate* Characteristic Age, yr^ <70 70 AJCC T stage^ T1–T3 T4 Grade of disease^ Low High PSA, ng/ml^ <20 20 AJCC N stage^ N0 N1 AJCC M stage^ M1a M1b M1c Adjusted SHR 95% confidence interval Fig. 2 – Survival of patients with metastatic prostate cancer (PCa) at diagnosis undergoing local therapy (LT) based on the number of factors independently associated with an increase in PCa-specific mortality: T4 or high-grade disease, age I70 yr, PSA I20 ng/ml, and pelvic lymphadenopathy. (A) Kaplan-Meier analysis demonstrating overall survival; (B) cumulative incidence of PCa-specific mortality, accounting for the competing risk of non-PCa and adjusted for race, American Joint Committee on Cancer M stage, year of diagnosis, and registry. Patients undergoing no surgery or radiation therapy (NSR) are listed as a reference. p value Ref 2.31 1.44–3.72 0.001 Ref 2.09 1.05–4.18 0.037 Ref 3.79 1.30–11.07 0.015 Ref 2.24 1.37–3.66 0.001 Ref 3.13 1.60–6.12 0.001 Ref 3.32 3.66 1.23–9.01 1.23–10.84 0.018 0.019 SHR = subhazard ratio; Ref = reference; AJCC = American Joint Committee on Cancer; PSA = prostate-specific antigen. Surveillance Epidemiology and End Results, 2004–2010. ^ At the time of diagnosis. * OS survival (38.2%; 95% CI, 24.4–51.9) and a DSS probability (50.1%) similar to NSR patients (Fig. 2). Subset analyses were performed to determine if survival differed among groups based on age (<70 vs 70 yr) or PSA (<20 vs 20 ng/ml), since previous studies have demonstrated poorer survival in metastatic disease in older patients (75 yr) [13,14] and in patients with PSA 20 ng/ml [15]. Although both OS and DSS probabilities were significantly higher in patients <70 yr, only OS was significantly better in patients 70 yr undergoing LT compared with NSR patients (Fig. 3 and Table 4). OS and DSS probability were significantly higher in RP or BT patients with PSA <20 ng/ml. However, although both RP and BT demonstrated a significantly higher OS in patients with PSA 20 ng/ml, only RP patients demonstrated significantly decreased CSM compared with NSR patients (Fig. 4 and Table 4). To determine if the extent of metastatic disease affected survival among groups, subset analyses were performed based on AJCC M stage (M1a–c) (Fig. 5 and Table 4). Compared with NSR patients, men undergoing RP exhibited decreased CSM regardless of M stage and a higher OS in M1b and M1c disease. In BT patients, OS was higher regardless of M stage, and CSM was decreased in men with M1c disease. There were no significant differences in survival among groups based on individual AJCC M stage in patients dying of non-PCa causes. 4. Discussion PCa is the most commonly diagnosed cancer and the second leading cause of death from cancer in American men. Historically, approximately 25% of men presented with 1062 EUROPEAN UROLOGY 65 (2014) 1058–1066 Table 4 – Subset analyses of survival of patients with metastatic prostate cancer at diagnosis based on age, prostate-specific antigen, or American Joint Committee on Cancer M stage and treatment received* Age, yr <70 NSR RP BT 70 NSR RP BT PSA, ng/ml <20 NSR RP BT 20 NSR RP BT AJCC M stage* M1a NSR RP BT M1b NSR RP BT M1c NSR RP BT No. (%) Adjusted SHR 95% CI p value 5-yr OS, % 95% CI DSS, yra p value 1 3 5 3324 (42.6) 202 (82.4) 74 (57.4) Ref 0.26 0.55 0.17–0.39 0.34–0.88 <0.001 0.014 28.9 71.2 57.4 26.6–31.3 61.6–78.9 22.6–66.6 <0.001 <0.001 86.1 96.7 92.2 57.7 86.9 73.9 45.8 82.0 65.2 5047 (57.6) 46 (17.3) 63 (43.5) Ref 0.65 0.67 0.37–1.12 0.43–1.03 0.120 0.070 18.1 50.3 48.5 16.5–19.8 30.1–67.5 30.0–64.7 <0.001 <0.001 80.1 86.7 86.2 58.6 70.8 69.9 49.5 63.5 62.5 No. (%) Adjusted SHR^ 5-yr OS, % 95% CI p value 95% CI p value DSS, yrb 1 3 5 1503 (21.9) 165 (77.1) 64 (53.8) Ref 0.26 0.36 0.15–0.45 0.18–0.72 <0.001 0.004 33.7 77.1 71.2 30.4–37.1 66.1–85.0 46.8–85.9 <0.001 <0.001 87.3 96.5 95.3 66.6 89.9 86.5 57.9 86.7 82.3 5373 (78.1) 49 (22.9) 55 (46.2) Ref 0.58 0.91 0.34–0.97 0.63–1.33 0.039 0.633 19.8 55.7 37.3 18.2–21.5 37.1–70.9 21.4–53.2 <0.001 0.027 81.4 88.8 82.9 55.6 71.3 58.5 44.8 63.0 48.1 No. (%) Adjusted SHR^ 5-yr OS, % 95% CI p value 95% CI p value DSS, yrc 1 3 5 463 (5.9) 24 (9.8) 16 (12.4) Ref 0.24 0.56 0.06–0.95 0.20–1.58 0.043 0.272 35.1 64.3 54.7 28.0–42.3 38.7–81.4 8.6–86.2 0.064 0.014 93.4 98.4 96.3 73.3 92.9 84.1 61.4 89.1 76.2 5469 (70.0) 150 (61.2) 75 (58.1) Ref 0.35 0.74 0.22–0.55 0.42–1.05 <0.001 0.078 22.9 70.1 55.0 21.2–24.6 58.1–79.2 31.1–64.5 <0.001 <0.001 84.1 94.1 89.2 59.6 83.4 71.0 48.4 77.6 61.9 1879 (24.1) 71 (29.0) 38 (29.5) Ref 0.33 0.56 0.19–0.57 0.34–0.94 <0.001 0.027 18.6 60.7 53.4 16.1–21.2 42.7–74.6 34.4–69.2 <0.001 <0.001 75.6 91.1 85.4 50.4 80.0 68.3 43.0 75.6 62.1 SHR = subhazard ratio; M1a = nonregional lymph nodes; M1b = bone metastasis with or without lymph nodes; M1c = distant metastasis with or without bone and lymph node involvement; OS = overall survival; CI = confidence interval; DSS = disease-specific survival; NSR = no surgery or radiation therapy; RP = radical prostatectomy; BT = brachytherapy; PSA = prostate-specific antigen; AJCC = American Joint Committee on Cancer; Ref = reference. * Based on multivariable competing risks regression analysis using death from non–prostate cancer as the competing variable. a Adjusted for race; registry; year of diagnosis; PSA; and AJCC T, N, and M stages. b Adjusted for age; race; registry; year of diagnosis; and AJCC T, N, and M stages. c Adjusted for age, race, registry, year of diagnosis, PSA, and AJCC T and N stages. either metastatic or lymph node–positive disease. However, because of PSA screening and associated stage migration, <5% of men currently present with synchronous metastatic disease [16]. Although RP and radiation therapy (BT, conformal radiation therapy, and intensity-modulated radiation therapy [IMRT]) are routinely used for the treatment of organ-confined or locally advanced disease, ADT remains the standard initial management for patients diagnosed with metastatic disease. Despite the ability of ADT to prolong survival and curtail disease-related symptoms, resistance to hormone therapy ultimately develops. The introduction of newer, more novel agents, including sipuleucel-T [17], abiraterone [18], cabazitaxel [19], and enzalutamide [20], has shown improvement in survival. However, 5-yr survival for men with metastatic disease is only 28%, in stark contrast to nearly 100% for men diagnosed without mPCa [21]. Decreasing tumor burden, through cytoreductive surgery, radiation, or both, improves survival in a number of malignancies. In particular, studies demonstrate that maximal cytoreduction improves survival in patients with breast cancer [5], colon cancer [3], and ovarian cancer [4], in addition to increasing tumor response to systemic chemotherapy. Furthermore, treatment of the primary tumor itself has been associated with improved survival in patients diagnosed with glioblastoma [8], colon cancer [9], and renal cell carcinoma [6,7]. Although prospective data do not exist regarding a survival benefit for patients with mPCa undergoing treatment of the primary tumor, there are retrospective EUROPEAN UROLOGY 65 (2014) 1058–1066 [(Fig._3)TD$IG] 1063 Fig. 3 – Overall survival (left column) and cumulative incidence of prostate cancer (PCa)-specific mortality (right column) in patients with metastatic PCa at diagnosis based on age ([A] <70 yr and [B] I70 yr) and treatment received. For cumulative incidence of cancer-specific mortality, analyses are adjusted for race; prostate-specific antigen; tumor grade; American Joint Committee on Cancer T, N, and M stages; year of diagnosis; and registry, and account for the competing risk of non–PCa death. NSR = no surgery or radiation therapy; RP = radical prostatectomy; BT = brachytherapy. [(Fig._4)TD$IG] Fig. 4 – Overall survival (left column) and cumulative incidence of prostate cancer (PCa)-specific mortality (right column) in patients with metastatic PCa at diagnosis based on prostate-specific antigen level ([A] <20 ng/ml and [B] I20 ng/ml) and treatment received. For cumulative incidence of cancerspecific mortality, analyses are adjusted for race; age; tumor grade; American Joint Committee on Cancer T, N, and M stages; year of diagnosis; and registry and account for the competing risk of non-PCa death. NSR = no surgery or radiation therapy; RP = radical prostatectomy; BT = brachytherapy (BT). 1064 [(Fig._5)TD$IG] EUROPEAN UROLOGY 65 (2014) 1058–1066 Fig. 5 – Overall survival (left column) and cumulative incidence of prostate cancer (PCa)–specific mortality (right column) in patients with metastatic PCa at diagnosis based on American Joint Committee on Cancer M stage [M1a, M1b, or M1c] and treatment received. For cumulative incidence of cancerspecific mortality, analyses are adjusted for age, race, prostate-specific antigen, tumor grade, AJCC T and N stages, year of diagnosis, and registry, and account for the competing risk of non-PCa death. NSR = no surgery or radiation therapy; RP = radical prostatectomy; BT = brachytherapy. studies that do indicate improved outcome with prostate tumor cytoreduction [22–24]. In particular, investigators at the Mayo Clinic evaluated 79 matched pairs of patients with pTxN+ PCa undergoing either RP with pelvic lymph node dissection (PLND) plus orchiectomy within 3 mo of surgery or PLND with orchiectomy only [23]. They found that patients undergoing RP with orchiectomy demonstrated both a higher OS (66% vs 28%; p < 0.001) and a higher DSS (79% vs 39%; p < 0.001) compared with patients undergoing orchiectomy alone [23]. In a population-based study using the Munich Cancer Registry, Engel et al. examined the OS and relative survival of patients with node-positive disease undergoing RP (n = 688) in comparison with patients in whom RP was aborted (n = 250) [24]. Recognizing that there was a higher number of positive lymph nodes in the aborted RP group, 10-yr OS (64% vs 28%) and relative survival (86% vs 40%) were still higher in the RP group. In addition, on multivariable analysis, not undergoing RP was an independent predictor of decreased survival (hazard ratio: 2.04; 95% CI, 1.59–2.63; p < 0.0001) [24]. Finally, studies have shown an increased response to ADT and newer agents (eg, sipuleucel-T) in patients with metastatic disease who had undergone prior RP [25–27]. To our knowledge, this is the first population-based analysis to suggest a possible survival benefit of primary treatment of the prostate in men diagnosed with mPCa. Our results demonstrate that patients undergoing definitive treatment of the prostate (either through RP or BT with or without adjuvant pelvic radiotherapy) had a higher 5-yr OS and DSS probability compared with patients not undergoing LT. It is important to note that in men who died of non-PCa causes, no survival differences were noted based on treatment compared with no treatment. We noted that features independently associated with increased CSM in patients undergoing LT included age 70 yr, high-grade and high-stage (T4) disease, PSA 20 ng/ml, and pelvic lymphadenopathy. Consistent with previous reports demonstrating poorer survival in patients with metastatic disease who were older or had a higher PSA, subset analyses in our study demonstrated that patients EUROPEAN UROLOGY 65 (2014) 1058–1066 70 yr and patients with PSA 20 ng/ml were less likely to benefit from LT [13–15]. In terms of AJCC T and N stages, although resection of bulky tumor or lymph nodes is certainly achievable, the potential for leaving disease behind is greater, which might negate any beneficial effects of primary tumor cytoreduction. Because of the small sample size of patients undergoing LT in the current study, questions regarding benefit with respect to modality (surgery vs radiation therapy) based on the previously described factors would be best answered in a prospective trial. Mechanisms underlying a survival benefit of cytoreductive treatment remain unknown. Possible explanations in mPCa include removing tumor-promoting factors and immunosuppressive cytokines; decreasing the total tumor burden and thus allowing for an improved response to ADT and/or chemotherapy; eliminating the primary source of the dissemination of metastatic cells; and/or eliminating the primary site, which data have indicated can also be a site of metastasis through the ‘‘self-seeding’’ hypothesis [28]. Studies have shown that increased circulating tumor cells are associated with tumor progression and reduced survival [29]. Removal of the prostate may therefore reduce the number of circulating tumor cells. Finally, the most significant findings from this study were that survival of patients undergoing LT was still improved regardless of the extent of metastases and that death from non-PCa causes did not differ among groups on the whole or based on AJCC M stage. Although the baseline expectation would be that the greatest benefit would be seen only in patients with M1a disease, not only was improved survival noted in patients with either M1b or M1c disease, but also the difference was most pronounced in patients with M1c disease. If true, this finding would be critical for patient enrollment in prospective clinical trials. SEER is the only comprehensive population-based database in the United States that includes disease stage and grade at the time of diagnosis, initial treatments performed, and accurate data regarding patient survival. As such, SEER represents an ideal approach to studying the survival of patients diagnosed with mPCa in the United States, especially in recent time periods. We chose to include only patients diagnosed between 2004 and 2010, as this time period represented the most up-to-date and comprehensive collection of validated data regarding PCa based on the Collaborative Staging System (eg, sites of metastasis, PSA, surgery-specific coding) and correlated with the most recent standard of care for patients with metastatic disease (eg, docetaxel-based chemotherapy and ADT). In fact, we noted that a more recent year of diagnosis was associated with decreased CSM in the entire cohort, likely representing the positive impact of improved agents. Nonetheless, variables unavailable from SEER undoubtedly limited our analysis and precluded controlling for any selection bias that might exist. These variables include patient performance status, comorbidity, site-specific EBRT codes, timing and dosage of chemotherapy and/or ADT, and the use of ADT relative to surgery or BT. The lack of ADT 1065 information is especially important given the influence of ADT on PCa progression and survival. Finally, SEER lacks information regarding the extent of bony metastasis, an entity that undoubtedly influences patient survival. 5. Conclusions Despite the inherent limitations of this SEER-based study, our results suggest that LT for the primary tumor confers a survival advantage in patients with mPCa at diagnosis. Because of the lack of site-specific EBRT codes, it was not possible to examine the effects of IMRT or other forms of prostate-directed EBRT on patient survival. However, we would hypothesize that dedicated treatment of the primary tumor by EBRT would confer similar survival benefits, since level 1 evidence has shown that ADT plus radiation therapy compared with ADT alone confers a survival advantage among patients with high-risk disease and an increased risk of micrometastases [30]. Although our results are based on data collected prospectively, our analyses are still retrospective, which limits our ability to fully conclude that localized treatment of the primary tumor should be part of the multidisciplinary management of patients with mPCa. As such, we do not advocate LT based on these data alone but instead in the context of organized prospective clinical trials designed not only to demonstrate a survival benefit with LT of the primary tumor but also to identify patients most likely to benefit. Author contributions: Stephen H. Culp had full access to all the data in the study and takes responsibility for the integrity of the data and the accuracy of the data analysis. Study concept and design: Culp, Schellhammer, Williams. Acquisition of data: Culp. Analysis and interpretation of data: Culp, Schellhammer, Williams. Drafting of the manuscript: Culp, Schellhammer, Williams. Critical revision of the manuscript for important intellectual content: Culp, Schellhammer, Williams. Statistical analysis: Culp. Obtaining funding: None. Administrative, technical, or material support: Culp, Schellhammer, Williams. Supervision: Culp, Schellhammer, Williams. Other (specify): None. Financial disclosures: Stephen H. Culp certifies that all conflicts of interest, including specific financial interests and relationships and affiliations relevant to the subject matter or materials discussed in the manuscript (eg, employment/affiliation, grants or funding, consultancies, honoraria, stock ownership or options, expert testimony, royalties, or patents filed, received, or pending), are the following: None. Funding/Support and role of the sponsor: None. References [1] Scardino P. Update: NCCN prostate cancer clinical practice guidelines. JNCCN 2005;3(Suppl 1):S29–33. [2] Loblaw DA, Virgo KS, Nam R, et al. Initial hormonal management of androgen-sensitive metastatic, recurrent, or progressive prostate cancer: 2006 update of an American Society of Clinical Oncology practice guideline. J Clin Oncol 2007;25:1596–605. 1066 EUROPEAN UROLOGY 65 (2014) 1058–1066 [3] Glehen O, Mohamed F, Gilly FN. Peritoneal carcinomatosis from [17] Small EJ, Schellhammer PF, Higano CS, et al. Placebo-controlled digestive tract cancer: new management by cytoreductive surgery phase III trial of immunologic therapy with sipuleucel-T (APC8015) and intraperitoneal chemohyperthermia. Lancet Oncol 2004;5: in patients with metastatic, asymptomatic hormone refractory 219–28. prostate cancer. J Clin Oncol 2006;24:3089–94. [4] Bristow RE, Tomacruz RS, Armstrong DK, Trimble EL, Montz FJ. [18] de Bono JS, Logothetis CJ, Molina A, et al. Abiraterone and increased Survival effect of maximal cytoreductive surgery for advanced survival in metastatic prostate cancer. N Engl J Med 2011;364: ovarian carcinoma during the platinum era: a meta-analysis. J Clin Oncol 2002;20:1248–59. 1995–2005. [19] de Bono JS, Oudard S, Ozguroglu M, et al. Prednisone plus cabazi- [5] Polychemotherapy for early breast cancer: an overview of the taxel or mitoxantrone for metastatic castration-resistant prostate randomised trials. Early Breast Cancer Trialists’ Collaborative cancer progressing after docetaxel treatment: a randomised open- Group. Lancet 1998;352:930–42. label trial. Lancet 2010;376:1147–54. [6] Flanigan RC, Salmon SE, Blumenstein BA, et al. Nephrectomy fol- [20] Scher HI, Fizazi K, Saad F, et al. Increased survival with enzaluta- lowed by interferon alfa-2b compared with interferon alfa-2b alone mide in prostate cancer after chemotherapy. N Engl J Med 2012; for metastatic renal-cell cancer. N Engl J Med 2001;345:1655–9. [7] Mickisch GH, Garin A, van Poppel H, de Prijck L, Sylvester R. Radical nephrectomy plus interferon-alfa-based immunotherapy compared with interferon alfa alone in metastatic renal-cell carcinoma: a randomised trial. Lancet 2001;358:966–70. [8] Nitta T, Sato K. Prognostic implications of the extent of surgical resection in patients with intracranial malignant gliomas. Cancer 1995;75:2727–31. 367:1187–97. [21] American Cancer Society. Cancer facts and figures 2013. Atlanta, GA: American Cancer Society; 2013. [22] Steuber T, Budaus L, Walz J, et al. Radical prostatectomy improves progression-free and cancer-specific survival in men with lymph node positive prostate cancer in the prostate-specific antigen era: a confirmatory study. BJU Int 2011;107:1755–61. [23] Ghavamian R, Bergstralh EJ, Blute ML, Slezak J, Zincke H. Radical [9] Temple LK, Hsieh L, Wong WD, Saltz L, Schrag D. Use of surgery retropubic prostatectomy plus orchiectomy versus orchiectomy among elderly patients with stage IV colorectal cancer. J Clin Oncol alone for pTxN+ prostate cancer: a matched comparison. J Urol 2004;22:3475–84. 1999;161:1223–7, discussion 1227–8. [10] Harlan LC, Hankey BF. The surveillance, epidemiology, and end- [24] Engel J, Bastian PJ, Baur H, et al. Survival benefit of radical prosta- results program database as a resource for conducting descriptive tectomy in lymph node-positive patients with prostate cancer. Eur epidemiologic and clinical studies. J Clin Oncol 2003;21:2232–3. Urol 2010;57:754–61. [11] Greene FL, Page DL, Fleming ID, et al. AJCC cancer staging handbook: [25] Swanson GP, Riggs M, Earle J. Failure after primary radiation or TNM classification of malignant tumors. ed. 6. New York, NY: Springer- surgery for prostate cancer: differences in response to androgen Verlag; 2002. [12] Fine JP, Gray RJ. A proportional hazards model for the subdistribution of a competing risk. J Am Stat Assoc 1999;94:496–509. [13] Humphreys MR, Fernandes KA, Sridhar SS. Impact of age at diagnosis on outcomes in men with castrate-resistant prostate cancer (CRPC). J Cancer 2013;4:304–14. [14] Scosyrev E, Messing EM, Mohile S, Golijanin D, Wu G. Prostate cancer in the elderly: frequency of advanced disease at presentation and disease-specific mortality. Cancer 2012;118:3062–70. ablation. J Urol 2004;172:525–8. [26] Thompson IM, Tangen C, Basler J, Crawford ED. Impact of previous local treatment of prostate cancer on subsequent metastatic disease. J Urol 2002;168:1008–12. [27] Kantoff PW, Higano CS, Shore ND, et al. Sipuleucel-T immunotherapy for castration-resistant prostate cancer. N Engl J Med 2010;363: 411–22. [28] Comen E, Norton L, Massague J. Clinical implications of cancer selfseeding. Nat Rev Clin Oncol 2011;8:369–77. [15] Bertaglia V, Tucci M, Fiori C, et al. Effects of serum testosterone [29] Resel Folkersma L, San Jose Manso L, Galante Romo I, Moreno Sierra levels after 6 months of androgen deprivation therapy on the J, Olivier Gomez C. Prognostic significance of circulating tumor cell outcome of patients with prostate cancer. Clin Genitourin Cancer count in patients with metastatic hormone-sensitive prostate can- 2013;11:325–30. cer. Urology 2012;80:1328–32. [16] Ryan CJ, Elkin EP, Small EJ, Duchane J, Carroll P. Reduced incidence [30] Warde P, Mason M, Ding K, et al. Combined androgen deprivation of bony metastasis at initial prostate cancer diagnosis: data from therapy and radiation therapy for locally advanced prostate cancer: PCaSURE. Urol Oncol 2006;24:396–402. a randomised, phase 3 trial. Lancet 2011;378:2104–11.